TRACHEOBRONCHOPATHIA OSTEOCHONDROPLASTICA- A CASE REPORT

KESHAVAN V VAMANANNAMPOOTHIRIK

Abstract


Tracheobronchopathica osteochondroplastica ia a rare disorder of the trachea and large airways. It is associated with the development of multiple osseous and cartilaginous nodules in the sub-mucosa of the airways.Patients commonly present with cough, hemoptysis and recurrent respiratory tract infections. The diagnosis is usually made with the help of CT scan and bronchoscopy. Bronchoscopic biopsy reveals the presence of cartilage and bone tissue.This condition usually remains stable for many years or progresses very slowly.There is no specific treatment described for this                                   condition. Only a minority of patients develop significant upper airway obstruction and require invasive treatment.We report a case of Tracheobronchopathia Osteochondroplastica in a 53 year old man from South India.

 


Full Text:

PDF

References


Vilkman S, Keistinen T. Tracheobronchopathia osteochondroplastica. Report of a young man with severe disease

and retrospective review of 18 cases. Respir Int Rev Thorac Dis. 1995;62(3):151–4.

Karlikaya C, Yüksel M, Kiliçli S, Candan LTracheobronchopathia osteochondroplastica. Respirol Carlton Vic. 2000 Dec;5(4):377–80.

Jabbardarjani HR, Radpey B, Kharabian S, Masjedi MR. Tracheobronchopathia osteochondroplastica: presentation of ten cases and review of the literature. Lung. 2008 Oct;186(5):293–7.

Mathlouthi A, Ben Rehouma C, Ben M’Rad S, Dumon JF, Labbene N, Driss B, et al. [Tracheobronchopathia osteochondroplastica. Personal observation and review of the literature]. Rev Pneumol Clin. 1993;49(3):156–62.

Prakash UBS. Tracheobronchopathia osteochondroplastica. Semin Respir Crit Care Med. 2002 Apr;23(2):167–75.

Kart L, Kiraz K, Büyükolan H, Ozesmi M, Sentürk Z, Gülmez I, et al. Tracheobronchopathia osteochondroplastica: two cases and review of literature. Tüberküloz Ve Toraks. 2004;52(3):268–71.

Sutor GC, Glaab T, Eschenbruch C, Fabel H. Tracheobronchopathia osteochondroplastica: an uncommon cause of retention pneumonia in an elderly patient. Pneumol Stuttg Ger. 2001 Dec;55(12):563–7.

Shigematsu Y, Sugio K, Yasuda M, Sugaya M, Ono K, Takenoyama M, et al. Tracheobronchopathia osteochondroplastica occurring in a subsegmental bronchus and causing obstructive pneumonia. Ann Thorac Surg. 2005 Nov;80(5):1936–8.

Härmä RA, Suurkari S. Tracheopathia chondro-osteoplastica. A clinical study of thirty cases. Acta Otolaryngol (Stockh). 1977 Aug;84(1-2):118–23.

Leske V, Lazor R, Coetmeur D, Crestani B, Chatté G, Cordier JF, et al. Tracheobronchopathia osteochondroplastica: a study of 41 patients. Medicine (Baltimore). 2001 Nov;80(6):378–90.

Tajima K, Yamakawa M, Katagiri T, Sasaki H. Immunohistochemical detection of bone morphogenetic protein-2 and transforming growth factor beta- 1 in tracheopathia osteochondroplastica. Virchows Arch Int J Pathol. 1997 Nov;431(5):359–63.

Meyer CN, Døssing M, Broholm H. Tracheobronchopathia osteochondroplastica. Respir Med. 1997 Sep;91(8):499–502.

Barthwal MS, Chatterji RS, Mehta A. Tracheobronchopathia osteochondroplastica. Indian J Chest Dis Allied Sci. 2004 Mar;46(1):43–6.

Willms H, Wiechmann V, Sack U, Gillissen A. Tracheobronchopathia osteochondroplastica: A rare cause of chronic cough with haemoptysis. Cough Lond Engl. 2008;4:4.

Coëtmeur D, Bovyn G, Leroux P, Niel-Duriez M. Tracheobronchopathia osteochondroplastica presenting at the time of a difficult intubation. Respir Med. 1997 Sep;91(8):496–8.

Smith DC, Pillai R, Gillbe CE. Tracheopathia osteochondroplastica. A cause of unexpected difficulty in tracheal intubation. Anaesthesia. 1987 May;42(5):536–8.

Zhang X-B, Zeng H-Q, Cai X-Y, Zhang Y-J. Tracheobronchopathia osteochondroplastica: a case report and literature review. J Thorac Dis. 2013 Oct;5(5): E182–184.

Nienhuis DM, Prakash UB, Edell ES. Tracheobronchopathia osteochondroplastica. Ann Otol Rhinol Laryngol. 1990 Sep;99(9 Pt 1):689–94.

Molloy AR, McMahon JN. Rapid progression of tracheal stenosis associated with tracheopathia osteo-chondroplastica. Intensive Care Med.

;15(1):60–2.

Abu-Hijleh M, Lee D, Braman SS. Tracheobronchopathia osteochondroplastica: a rare large airway disorder. Lung. 2008 Dec;186(6):353–9.


Refbacks

  • There are currently no refbacks.


Creative Commons License
This work is licensed under a Creative Commons Attribution-NoDerivatives 4.0 International License.

An initiative of The Tamil Nadu Dr M.G.R. Medical University